Berek Novak's Gyn 2019. Chapter 16 Intraepithelial Disease of the Cervix, Vagina, and Vulva

 CHAPTER 16

Intraepithelial Disease of the Cervix, Vagina, and Vulva

KEY POINTS

1 The criteria for the diagnosis of intraepithelial neoplasia may vary according to the

pathologist, but the significant features are cellular immaturity, cellular

disorganization, nuclear abnormality, and increased mitotic activity.

2 Metaplasia advances from the original squamocolumnar junction (SCJ) inward,

toward the external os and over the columnar villi to establish the transformation

zone. Cervical intraepithelial neoplasia (CIN) typically originates in the

transformation zone at the advancing SCJ.

3 Infection with human papillomavirus (HPV) is the primary cause of cancer of the

cervix and its precursor lesions. Persistent high-risk oncogenic HPV infection is the

principal risk factor for the development of CIN. In the vast majority of cases, HPV

infection will clear in 9 to 15 months.

4 Specific high-risk HPV types account for about 90% of high-grade intraepithelial

lesions and cancer (HPV-16, -18, -31, -33, -35, -39, -45, -51, -52, -56, -58, -59, and

-68). HPV-16 is the most common HPV found in invasive cancer and in CIN 2 and

CIN 3. Malignant transformation requires the expression of E6 and E7 HPV

oncoproteins.

5 High-risk HPV testing is a critical component of the triage for equivocal (ASC-US)

cytology, as a component of co-testing with simultaneous cytology, and as a standalone primary screening modality.

6 Evidence-based guidelines recommend that cervical cancer screening not begin until

age 21 years, regardless of sexual history. For women 21 to 29 years, the

recommendation is screening with cytology every 3 years. From 30 to 65 years cotesting with conventional cytology and high-risk HPV testing every 5 years or

cytology alone every 3 years are appropriate alternatives. After the age of 65 it is

911appropriate to discontinue screening in women with a negative screening history as

documented by either 3 negative cytology results or 2 negative co-tests in the

previous 10 years.

7 The usefulness of high-risk HPV testing in the assessment of atypical squamous cells

of unknown significance (ASC-US) Pap test results is well established, and aids in

the identification of 90% of the patients with CIN 2 or 3 lesions.

8 Women with atypical squamous cells-high grade (ASC-H) should be referred to

colposcopy because of the underlying risk of CIN 2 and/or 3, and should not be

triaged with high-risk HPV testing.

9 Colposcopy is required for the evaluation of a low-grade squamous intraepithelial

lesion (LSIL) cytology. Any woman with a cytology consistent with high-grade

squamous intraepithelial lesion (HSIL) must undergo colposcopy and directed

biopsy.

10 The minimum elements of a comprehensive colposcopic examination include

visualization of squamocolumnar junction, identification of acetowhitening or other

lesion(s), and an overall colposcopic impression (normal/benign, low grade, high

grade, cancer).

11 It is a best practice for pathologists and colposcopists to review jointly the

colposcopic examination findings, cytology, molecular testing, cervical biopsy, and

endocervical sampling in order to develop a therapeutic and surveillance plan.

12 The evidence-based guidelines for the management of cervical cytologic and

histologic entities lend themselves to structured clinical algorithms that are available

for download from the Web (www.asccp.org), on various mobile phone

applications, and may be incorporated into a variety of electronic health record

platforms.

13 CIN 1 is a histopathologic manifestation of HPV infection, not a cancer precursor.

For CIN 1 that persists for 24 months or more, a patient with an adequate

colposcopic examination may be given the choice of continued surveillance or

destruction of the transformation zone with ablation or excision.

14 CIN 2 and CIN 3 lesions are neoplastic precursors and grouped for the purposes of

diagnostic reporting and treatment. Women, 25 years of age and older, with

adequate colposcopy and histologic documentation of CIN 2 and/or CIN 3 require

destruction or excision of the transformation zone.

15 Although CIN 2 and CIN 3 can be treated with a variety of outpatient techniques,

the preferred treatment is LEEP. Ablative therapy using cryotherapy, laser ablation,

or any other technique is not appropriate if there is evidence of microinvasive or

invasive cancer on cytology, colposcopy, endocervical curettage (ECC), or biopsy.

16 Adenocarcinoma in situ (AIS) is a cancer precursor, and the preferred management

for women who have completed childbearing and have a histologic diagnosis of AIS

on a specimen from a diagnostic excisional procedure is hysterectomy.

17 Loop excision should not typically be used before a high-grade intraepithelial lesion

is identified with histopathology. However, treatment after an HSIL cytology may

912be appropriate among populations for whom colposcopic follow-up is not possible.

18 Conization is indicated for diagnosis in women with CIN 3 or atypical glandular cell

(AGC)-adenocarcinoma in situ, but hysterectomy is the treatment of last resort for

recurrent high-grade CIN.

19 Women with persistent abnormal cytology without evident cervical pathology and

those with abnormal cytology after treatment of CIN should be examined carefully

for vaginal intraepithelial neoplasia (VAIN). VAIN 1/HPV or VAIN 2 does not

require treatment and may be managed with surveillance. VAIN 3 lesions that are

adequately sampled to rule out invasive disease can be treated with laser therapy or

excisional therapy.

20 Vulvar intraepithelial neoplasia (VIN) 3 is a neoplastic precursor and can be

unifocal or multifocal. The therapeutic alternatives for VIN 3 are simple excision,

laser ablation, and superficial vulvectomy.

CERVICAL INTRAEPITHELIAL NEOPLASIA

The concept of preinvasive disease of the cervix was introduced in 1947, when

pathologists identified features suggestive of invasive cancer but confined to

epithelium (1). Subsequent studies showed that these lesions left untreated could

progress to cervical cancer (2). Improvements in cytologic assessment led to the

identification of early precursor lesions known as dysplasia, a term that connotes

the malignant potential of these lesions. Historically, carcinoma in situ (CIS) was

treated very aggressively (most often with hysterectomy), whereas dysplasias

were believed to be less significant and were not treated or were treated by

colposcopic biopsy and cryosurgery. The concept of cervical intraepithelial

neoplasia (CIN) was introduced in 1968, when Richart suggested that dysplasias

have the potential for progression (3). [1] The criteria for the diagnosis of

intraepithelial neoplasia may vary according to the pathologist, but the

significant features are cellular immaturity, cellular disorganization, nuclear

abnormality, and increased mitotic activity. The extent of the mitotic activity,

immature cellular proliferation, and nuclear atypia identifies the degree of

neoplasia. If the presence of mitoses and immature cells is limited to the lower

third of the epithelium, the lesion usually is designated as CIN 1. Involvement of

the middle and upper thirds is diagnosed as CIN 2 and CIN 3, respectively (Fig.

16-1).

Cervical Anatomy

The cervix is composed of columnar epithelium, which lines the endocervical

canal, and squamous epithelium, which covers the exocervix (4). The point at

which they meet is called the squamocolumnar junction (SCJ) (Figs. 16-2 and 16-

9133).

The Squamocolumnar Junction

The SCJ is not restricted to the external os. Instead, it is a dynamic point that

changes in response to puberty, pregnancy, menopause, and hormonal stimulation

(Fig. 16-4). In neonates, the SCJ is located on the exocervix. At menarche, the

production of estrogen causes the vaginal epithelium to fill with glycogen.

Lactobacilli act on the glycogen to lower the pH, stimulating the subcolumnar

reserve cells to undergo metaplasia (4).

[2] Metaplasia advances from the original SCJ inward, toward the external

os and over the columnar villi to establish the transformation zone. The

transformation zone extends from the original SCJ to the physiologically active

SCJ, as demarcated by the SCJ. As the metaplastic epithelium in the

transformation zone matures, it begins to produce glycogen and eventually

resembles the original squamous epithelium, both colposcopically and

histologically (Fig. 16-5A,B).

CIN typically originates in the transformation zone at the advancing SCJ.

The anterior lip of the cervix is twice as likely to develop CIN as the posterior lip,

and CIN rarely originates in the lateral angles. Once CIN occurs, it can progress

horizontally to involve the entire transformation zone, but it usually does not

replace the original squamous epithelium. This progression usually results in CIN

with a sharp external border. Proximally, CIN involves the cervical clefts, and this

area tends to have the most severe CIN lesions. The extent of involvement of

these cervical glands has significant therapeutic implications since the entire

gland must be destroyed to ensure elimination of the CIN (4). The only way to

determine where the original SCJ was located is to look for nabothian cysts or

cervical cleft openings, which indicate the presence of columnar epithelium. After

the metaplastic epithelium matures and forms glycogen, it is called the healed

transformation zone and is relatively resistant to oncogenic stimuli.

914FIGURE 16-1 Diagram of cervical intraepithelial neoplasia compared with normal

epithelium.

The entire SCJ with early metaplastic cells is susceptible to oncogenic factors,

which may cause these cells to transform into CIN. Changes associated with CIN

are most likely to begin either during menarche or after pregnancy, when

metaplasia is most active. Conversely, after menopause a woman undergoes little

metaplasia and is at a lower risk of developing CIN from de novo human

papillomavirus (HPV) infection. HPV infection occurs through sexual contact in

general and intercourse in particular. Although several agents, including sperm,

seminal fluid histones, trichomonas, chlamydia, and herpes simplex virus, were

studied, it is well established that persistent high-risk oncogenic HPV infection

is the overwhelming risk factor for the development of CIN.

915FIGURE 16-2 The cervix and the transformation zone.

Normal Transformation Zone

916FIGURE 16-3 Diagram of the cervix and the endocervix.

The original squamous epithelium of the vagina and exocervix has four layers (4):

1. The basal layer is a single row of immature cells with large nuclei and a small

amount of cytoplasm.

2. The parabasal layer includes two to four rows of immature cells that have

normal mitotic figures and provide the replacement cells for the overlying

epithelium.

3. The intermediate layer includes four to six rows of cells with larger amounts

of cytoplasm in a polyhedral shape separated by an intercellular space.

Intercellular bridges, where differentiation of glycogen production occurs, can

be identified with light microscopy.

4. The superficial layer includes five to eight rows of flattened cells with small

uniform nuclei and a cytoplasm filled with glycogen. The nucleus becomes

pyknotic, and the cells detach from the surface (exfoliation). These cells form

the basis for Papanicolaou (Pap) testing more accurately known as cervical

cytology.

917FIGURE 16-4 Different locations of the transformation zone and the squamocolumnar

junction during a woman’s lifetime. The arrows mark the active transformation zone. The

blue arrows indicate internal boundaries of SCJ. The white arrows indicate external

boundaries of the SCJ.

918919FIGURE 16-5 A: Active metaplasia in the transformation zone. B: Maturing metaplasia in

the transformation zone.

Columnar Epithelium

Columnar epithelium has a single layer of columnar cells with mucus at the top

and a round nucleus at the base. The glandular epithelium is composed of

numerous ridges, clefts, and infoldings and, when covered by squamous

metaplasia, leads to the appearance of gland openings. Technically, the

endocervix is not a gland, but often the term gland openings is used.

Metaplastic Epithelium

Metaplastic epithelium, found at the SCJ, begins in the subcolumnar reserve cells.

Under stimulation of lower vaginal acidity, the reserve cells proliferate, lifting the

columnar epithelium. The immature metaplastic cells have large nuclei and a

small amount of cytoplasm without glycogen. As the cells mature normally, they

produce glycogen, eventually forming the four layers of epithelium. The

metaplastic process begins at the tips of the columnar villi, which are exposed

first to the acid vaginal environment. As the metaplasia replaces the columnar

epithelium, the central capillary of the villus regresses, and the epithelium flattens

out, leaving the epithelium with its typical vascular network. As metaplasia

proceeds into the cervical clefts, it replaces columnar epithelium and similarly

flattens the epithelium. The deeper clefts may not be completely replaced by the

metaplastic epithelium, leaving mucus-secreting columnar epithelium trapped

under the squamous epithelium. Some of these glands open onto the surface;

others are completely encased, with mucus collecting in nabothian cysts. Gland

openings and nabothian cysts mark the original SCJ and the outer edge of the

original transformation zone (Fig. 16-5A,B) (4).

920FIGURE 16-6 Cervical intraepithelial neoplasia grade 1 (CIN 1) with koilocytosis. The

normal maturation process and differentiation from the basal and parabasal layers to the

intermediate and superficial layers are maintained. In the upper layers, koilocytes are

characterized by perinuclear halos, well-defined cell borders, and nuclear hyperchromasia,

irregularity, and enlargement.

Human Papillomavirus

The cytologic changes of HPV were first recognized by Koss and Durfee in 1956

and given the term koilocytosis (5). Their significance was not recognized until 20

years later, when Meisels et al. reported these changes in mild dysplasia (Fig. 16-

6) (6). Molecular biologic studies showed high levels of HPV DNA and capsid

antigen, indicating productive viral infection in these koilocytic cells (7). HPVrelated changes are found in all grades of cervical neoplasia (8). [3] Infection

with HPV is the primary cause of cancer of the cervix and its precursor

lesions (9). As the CIN lesions become more severe (Fig. 16-7), the koilocytes

disappear, the HPV copy numbers decrease, and the capsid antigen disappears,

indicating that the virus is not capable of reproducing in less differentiated cells

(10). Instead, portions of the HPV DNA become integrated into the host cell.

Integration of the transcriptionally active DNA into the host cell appears to be

essential for malignant transformation (11). Malignant transformation requires

921the expression of E6 and E7 HPV oncoproteins (12). Because HPV will not

grow in cell culture, there is no direct evidence of the carcinogenesis of HPV.

However, a cell culture system for growing keratinocytes was described that

allows for stratification and differentiation of specific keratinase types (13). When

normal cells are transfected with the plasmid-containing HPV-16, the transfected

cells produce cytologic abnormalities identical to those seen in intraepithelial

neoplasia. The E6 and E7 oncoproteins are identifiable in the transfected cell

lines, providing strong laboratory evidence of a cause-and-effect relationship (14).

Cervical cancer cell lines that contain active copies of HPV-16 or -18 (SiHa,

HeLa, C 4–11, Ca Ski) express HPV-16 E6 and E7 oncoproteins (15).

HPV DNA can be detected in the overwhelming majority of women with

cervical neoplasia (16,17). There are more than 120 types of HPV identified, with

30 of these HPV types primarily infecting the squamous epithelium of the lower

anogenital tract of men and women (18,19). Detection of HPV is associated with

a 250-fold increase in risk of high-grade CIN (20). The percentage of

intraepithelial neoplasia attributed to HPV infection approaches 90% (17).

Specific high-risk HPV types account for about 90% of high-grade

intraepithelial lesions and cancer (HPV-16, -18, -31, -33, -35, -39, -45, -51,

-52, -56, -58, -59, and -68) (17). [4] HPV-16 is the most common HPV found

in invasive cancer and in CIN 2 and CIN 3 (21). It is the most common HPV

type found in women with normal cytology.

HPV-16 infection is not a very specific finding and can be found in 16% of

women with low-grade lesions and in up to 14% of women with normal cytology.

HPV type-18 is found in 23% of women with invasive cancers, 5% of women

with CIN 2 and CIN 3, 5% of women with HPV and CIN 1, and fewer than 2% of

patients with negative findings (17). Therefore, HPV-18 is more specific than

HPV-16 for invasive tumors.

Usually, HPV infections are typically transient and those that do persist may

remain latent for many years. Most women who are exposed have no clinical

evidence of disease, and the infection is eventually suppressed or eliminated (16).

Other women exhibit low-grade cervical lesions that mostly regress

spontaneously. [3] In the vast majority of cases, HPV infection will clear in 9

to 15 months (22). A small minority of women exposed to HPV develops

persistent infection that may progress to CIN (16,23). Persistent high-risk HPV

infection increases the risk of high-grade disease 300-fold and is required for the

development and maintenance of CIN 3 (24,25). Factors that may have a role in

persistence and progression include smoking, contraceptive use, infection with

other sexually transmitted diseases, or nutrition (16,21). Any factor that

influences the integration of HPV DNA into the human genome may contribute to

progression to invasive disease (26).

922FIGURE 16-7 Cervical biopsy showing normal cells, cervical intraepithelial neoplasia 2

and 3 (CIN 2, CIN 3). In CIN 3, the normal maturation is lost.

Screening

Cervical Cytology

Cervical cytology has been the mainstay of cervical cancer screening since the

mid-20th century. Its terminology has evolved to reflect an evolving and

improved understanding of the pathogenesis of HPV-related disease in the lower

genital tract. In 1988, the first National Cancer Institute (NCI) workshop held in

Bethesda, Maryland, resulted in the development of the Bethesda System for

cytologic reporting. That standardized method of reporting cytology findings

facilitated peer review and quality assurance and was updated and refined in the

Bethesda III System (2001) (Table 16-1).

According to this system, potentially premalignant squamous lesions fall into

specific categories: (i) atypical squamous cells (ASC), (ii) low-grade squamous

intraepithelial lesions (LSILs), and (iii) high-grade squamous intraepithelial

lesions (HSILs) (27). The ASC category is subdivided into two categories: those

of unknown significance (ASC-US) and those in which high-grade lesions must

be excluded (ASC-H). LSILs include CIN 1 (mild dysplasia) and the changes of

923HPV, termed koilocytotic atypia. The HSIL category includes CIN 2 and CIN 3

(moderate dysplasia, severe dysplasia, and CIS). The terminology, AGUS, or

atypical glandular cells of undetermined significance, was developed to

characterize evidence of nonsquamous glandular neoplasia originating in the

cervix.

Cellular changes associated with HPV (i.e., koilocytosis and CIN 1) are

included within the category of LSIL because the natural history, distribution of

various HPV types, and cytologic features are the same (26). Histopathologic and

molecular virologic correlation showed a similar heterogeneous distribution of

low- and high-risk HPV types in both koilocytosis and CIN 1 (28,29). On the

basis of clinical behavior, molecular biologic findings, and morphologic features,

HPV changes and CIN 1 are the same disease. The rationale for combining CIN 2

and CIN 3 into the category of HSIL is similar. The biologic studies reveal a

comparable mix of high-risk HPV types in the two lesions, and the separation of

the lesions is not reproducible (29,30). The management of CIN 2 and CIN 3 is

similar.

Cervical Cytologic Screening Test Accuracy

Screening for cervical cancer precursors using exfoliative cervicovaginal

cytology, the Pap test, was successful in reducing the incidence of cervical cancer

by 79% and the mortality by 70% since 1950 (31). The annual incidence rate

dropped from 8 to 5 cases per 100,000 women, so approximately 8,200 women

per year are diagnosed with cervical cancer (31–33). A literature review of

cervical cytology testing techniques was conducted by the Agency for Healthcare

Research and Quality (34). The conclusion was that the sensitivity of

conventional cytologic testing in detecting cervical cancer precursor lesions was

51%, with an estimated false-negative rate of 49%. In three reviews of the

accuracy of cervical cytology assessment, the sensitivity of the cervical cytology

for the detection of CIN 2 or 3 ranged from 47% to 62% and the specificity

ranged from 60% to 95% (35–37). More than half of all cases of invasive

cancer occur in women who were never screened or who were underscreened.

The causes of missed cases of cervical cancer in women who have been screened

are errors of sampling, fixation, interpretation or lack of follow-up (38).

Conventional cytology has improved in order to reduce false-negative errors.

Sampling errors occur because a lesion is too small to exfoliate cells or the device

did not pick up the cells and transfer them to the fixation media. Historically,

preparation errors occurred because of poor fixation on the glass slide, leading to

air drying and its consequences for interpretation. The slide preparations could be

too thick and obscured by vaginal discharge, blood, or mucus. These problems

were obviated with the widespread utilization of liquid-based media. Interpretive

924errors have been reduced by the large scale implementation of automated

detection devices that assist the cytotechnologist in identifying significant cellular

abnormalities. The ubiquitous use of liquid-based medium to collect the cytologic

sample and preserve the collected cervical cells significantly decreased specimen

sampling and preparation errors. With this technique, liquid samples are

processed to provide a uniform, thin layer of cervical cells without debris on a

glass slide. The cell sample is collected with an endocervical brush used in

combination with a plastic spatula or with a plastic broom. The sample is rinsed

in a vial containing liquid alcohol-based preservative. With this technique, 80% to

90% of the cells are transferred to the liquid media, as compared with the 10% to

20% transferred to the glass slide with conventional cytologic testing. Use of

liquid-based media eliminates air drying. The cells are retrieved from the vial by

passing the liquid through a filter, which traps the larger epithelial cells,

separating them from the small blood and inflammatory cells. This process yields

a thin layer of diagnostic cells properly preserved and more easily interpreted by

the cytologist. This technique reduces by 70% to 90% the rate of unsatisfactory

samples encountered with conventional cytologic testing (39). Liquid-based

cytology is commonly performed by most of the laboratories in the United States.

Another technology approved by the Food and Drug Administration (FDA) for

primary screening and rescreening samples of cervical cytology initially

interpreted as normal is the automated image-guided slide screening system. This

technique uses an automated microscope coupled to a special digital camera. The

system scans the slide and uses computer imaging techniques to analyze each

field of view on the slide. Computer algorithms rank each slide on the probability

that the sample may contain an abnormality. The selected slides are reviewed by a

cytotechnologist or cytopathologist. This technique reduced the false-negative

rate by 32% (40).

Human Papillomavirus Testing in Screening

An improved understanding of the critical role of high-risk human papillomavirus

infection in the development of cervical cancer and its precursors has generated

the proliferation of molecular tools that have come into clinical practice. Such

methods have undergone extensive clinical trials, have been submitted to the

rigorous approval process of the FDA, and have resulted in their licensure for

specific roles in the screening process. [5] High-risk HPV testing is a critical

component of the triage for equivocal (ASC-US) cytology, as a component of

co-testing with simultaneous cytology, and as a stand-alone primary

screening modality (Table 16-2).

Cervical Cancer Screening Recommendations

925Guidelines based on the literature were developed to guide cervical cancer

screening, follow-up, and treatment. The evolving state of the science and our

improved understanding of HPV and cervical carcinogenesis, and clinical practice

and liability considerations, occasionally lead to subtle differences in the

interpretation of these guidelines. Ultimately, guidelines cannot substitute for an

informed discussion of risks and benefits between a patient and health care

provider in order to make decisions about treatment.

The American College of Obstetricians and Gynecologists (ACOG) updated its

guidelines (41). [6] The ACOG recommends that women not initiate cervical

cancer screening until they are 21, regardless of the onset of sexual activity. This

acknowledges the very low prevalence of invasive cancer in very young women,

the long multiyear process of cervical carcinogenesis, and the very low but real

risks for preterm birth associated with outpatient excisional procedures. Likewise,

screening frequency was revised to every 2 years from ages 21 to 29 (with either

conventional slide or liquid-based cytology), and every 3 years for women after

age 30 years if 3 consecutive negative, that is, negative for intraepithelial lesion or

malignancy (NILM) Pap tests can be documented. More frequent screening

continues to be recommended for HIV-positive women (twice first year and

annually after), those who are immune suppressed, diethylstilbestrol (DES)

daughters, and for those with a history of CIN 2 or greater (screen annually for 20

years). Discontinuation of screening is reasonable between 65 and 70 years, with

reassessment of risk factors annually to determine if reinitiating screening is

appropriate. Likewise, in the setting of posthysterectomy for benign indications it

is reasonable to discontinue screening in the absence of a history of high-grade

CIN or cancer (Table 16-3).

Table 16-2 Commercially Available High-Risk HPV Assays and Their FDAApproved Clinical Indications

926Table 16-3 Comparison of Screening Guidelines From the American Cancer Society,

American Society of Colposcopy and Cervical Pathology and American

Society Clinical Pathology, the American College of Obstetricians and

Gynecologists, and the U.S. Preventive Services Task Force

The 2011 American Society for Colposcopy and Cervical Pathology (ASCCP),

American Cancer Society (ACS), and the American Society for Clinical

Pathology (ASCP) co-convened a guidelines development process in

collaboration with more than 21 partner organizations. The goal of this process

was to develop a set of updated evidence-based screening guidelines that reflected

our best understanding of the science (42). Contemporaneously and independent

of this effort the U.S. Preventive Services Task Force (USPSTF) is using an

entirely different methodology and on the basis of an independent systematic

evidence review in the process of updating that entity’s cervical cancer screening

recommendations (43). These near-parallel processes produced a set of

remarkably concordant recommendations whose uniformity has been beneficial to

patients and clinicians.

[6] These evidence-based guidelines recommend that cervical cancer

screening not begin until age 21 years, regardless of sexual history. For

women 21 to 29 years, the recommendation is screening with cytology every

3 years. From 30 to 65 years co-testing with conventional cytology and highrisk HPV testing every 5 years or cytology alone every 3 years are

appropriate alternatives. After the age of 65 it is appropriate to discontinue

screening in women with a negative screening history as documented by

either 3 negative cytology results or 2 negative co-tests in the previous 10

years (42,43).

927The USPSTF published its updated draft guidelines and made them available

for stakeholder input (Table 16-3). The major and historic innovation is the

unprecedented incorporation of primary screening using molecular high-risk HPV

testing (as an alternative to cytology every 3 years) in women between 30 and 65

years.

Atypical Squamous Cells

The ASC category does not include benign, reactive, and reparative changes,

classified as normal in the Bethesda system. This cytologic diagnosis is relatively

common, ranging from 3% to 25% in some centers (44). When standardized

diagnostic criteria are used, the rate of ASC results should be 3% to 5% (45). The

ASC category is subdivided into ASC-US and ASC-H.

The cytologic diagnosis of ASC-US is associated with a 10% to 20% incidence

of CIN 1 and a 3% to 5% risk for CIN 2 or 3 (46–49). CIN 1 is most often a

benign HPV infection and will regress spontaneously in more than 60% of cases;

therefore, the goal of triage of an ASC-US Pap test result is to identify more

advanced CIN 2 and CIN 3 lesions (50).

Immediate colposcopy is assumed to be the most sensitive method of detecting

CIN 2 or 3 (46,49). Because 80% of patients will not have significant lesions, it is

important to avoid overinterpretation of the colposcopic findings. [7] The

usefulness of high-risk HPV testing in the assessment of ASC-US Pap test

results (51–53) is well established, and aids in the identification of 90% of the

patients with CIN 2 or 3 lesions. To compare the aforementioned triage method

in a prospective, randomized fashion, the NCI funded an ASC-US/LSIL Triage

Study (ALTS) (54). Patients with ASC-US or LSIL were randomized to three

triage arms: (i) immediate colposcopy, (ii) HPV test, and (iii) conservative

management by repeat Pap test. There were 1,163 women in the immediate

colposcopy group, and 14 refused the examination. The results of colposcopy are

assumed to reflect the prevalent disease rates, which were as follows: CIN 1,

14.3%; CIN 2, 16.1%; and CIN 3, 5%. Thus, 75% of the women with ASC-US

had negative colposcopy results and either did not have a biopsy (25%) or had a

biopsy with negative results. The HPV test results were positive in 56.1% of the

patients, and 6.1% of the patients did not return for colposcopy. Of the 494 who

underwent colposcopy, the results were as follows: CIN 1, 22.5%; CIN 2, 11.9%;

and CIN 3, 15.6%. The sensitivity of HPV test was 95.9% for the detection of

CIN 2 and 96.3% for the detection of CIN 3.

In the conservatively managed group, only one follow-up cytology was

reported. The results of the single follow-up Pap test were included. Using a

cutoff that includes any positive finding of ASC-US or greater, the sensitivity is

85% for CIN 2 and 85.3% for CIN 3, with 58.6% of patients referred for

928colposcopy. If LSIL is used as a cutoff, 26.2% of the patients are referred, with

sensitivity of 64.0% for both CIN 2 and CIN 3. Using HSIL as the cutoff, 6.9%

are referred, and the sensitivity falls to 44%. The conclusion of the ALTS trial is

that HPV triage is highly sensitive in identifying CIN 2 and CIN 3 lesions and

that it cuts the rate of referral for colposcopy by approximately one-half (55).

When mathematical models are used to simulate the natural history of HPV and

cervical cancer in a cohort of US women, a 2- to 3-year screening strategy using

cytology with reflex high-risk HPV triages is more effective and less costly in

reducing the rate of cancer than annual conventional cytology (56).

[8] Women with ASC-H should be referred to colposcopy because of the

underlying risk of CIN 2 and/or 3, and should not be triaged with high-risk

HPV testing.

Low-Grade Squamous Intraepithelial Lesions

The cytologic diagnosis of LSIL is reproducible and accounts for 1.6% of

cytologic diagnoses (45). About 75% of the patients have CIN, with 20% being

CIN 2 or 3 (46–48). These patients require additional evaluation. The ALTS trial

closed the HPV test arm early because the HPV positivity rate was 82% and was

not a valid discriminator in determining the presence of disease. The ALTS trial

found that a cytology interpretation of LSIL is associated with a 25% risk of

histologic CIN 2 or 3 within 2 years. No effective triage strategy was identified to

spare many women from colposcopic referral without increasing their risk of CIN

3 and invasive carcinoma (57). [9] Guidelines reaffirm the appropriateness of

colposcopy to evaluate after an LSIL cytology (52).

High-Grade Squamous Intraepithelial Lesions

[9] Any woman with a cytologic specimen suggesting the presence of HSIL

must undergo colposcopy and directed biopsy (52). Two-thirds of patients with

this cytologic finding will have CIN 2 or greater. After colposcopically directed

biopsy and determination of the distribution of the lesion, excisional or ablative

therapy that addresses the entire transformation zone should be performed. For

populations who have completed childbearing and who are likely to be lost to

follow-up, outpatient excision of the transformation may be considered after this

cytologic diagnosis.

Colposcopic Diagnosis

The ASCCP convened a process to develop evidence-based and expert consensus

recommendations for the practice of colposcopy in the United States (58). An

outcome of this process was the development of standardized terminology for

929findings at colposcopic examination (59). It described [10] the minimum

elements of a comprehensive colposcopic examination, which include

visualization of SCJ, the identification of acetowhitening or other lesion(s),

and an overall colposcopic impression (normal/benign, low grade, high

grade, cancer) (Table 16-4) (59,60).

Table 16-4 Essential Elements of a Colposcopic Examination (Adapted from ASCCP)

Component Content

Precolposcopic

assessment

Evaluate/document the following: Indication; history of prior

screening tests, colposcopy, and treatment; parity, contraception,

pregnancy, menopause, hysterectomy, smoking, HIV, HPV

vaccination.

Informed consent.

Examination Gross assessment of the vulva, vagina, perianal area, and cervix.

Examination of the cervix and upper vagina with magnification after

application of 3–5% acetic acid using white light and green/blue filter.

Documentation Document cervix visibility, and visualization of squamocolumnar

junction.

Document (using diagram or photography) findings including

presence, location, size, appearance, and characteristic of the lesion.

Colposcopic impression.

Tissue

sampling

Perform/document biopsy type, location of lesions.

Perform/document endocervical sampling.

Postprocedure Document modality and timing of how patient will be notified.

The guidelines formalize the practice of risk-based colposcopy. In general,

colposcopists are asked to consider at least two and up to four biopsies of all

suspected lesions (61). For women at the lowest risk of high-grade disease (those

with less than HSIL cytology, no evidence for HPV16/18, and a normal

colposcopic impression), random non-targeted biopsies are not recommended.

Conversely, nonpregnant women at the greatest risk of disease may merit a more

aggressive diagnostic workup.

The p16 protein is a cell cycle regulator, and under physiologic conditions, p16

acts as an inhibitor of cyclin-dependent kinases CDK4 and CDK6; this leads to

cell cycle arrest in epithelial cells undergoing cellular differentiation. However, in

response to a transforming infection by high-risk human papillomavirus (hrHPV)

930with overexpression of oncogenic protein E7, p16 levels rise. The excess p16 is

thus a surrogate marker of the transforming HPV infection. p16 is

recommended for use as an adjudication tool for cases in which there is a

professional disagreement in histologic specimen interpretation, with the

caveat that the differential diagnosis includes a precancerous lesion (CIN 2/-

IN2 or CIN 3/-IN3) (62,63).

The 2012 ASCCP consensus guidelines recommended grouping CIN 2 and

CIN 3 together as high-grade histology. However, it was recognized that

there was a subset of CIN 2 patients that would not progress and thus did not

need treatment. In 2012, the College of American Pathologists and ASCCP

cosponsored the Lower Anogenital Squamous Terminology (LAST)

standardization project and published the LAST recommendations for

histopathology reporting of HPV-related squamous lesions of the lower

anogenital tract. Specifically LAST calls for the use of a 2-tier nomenclature

(low-grade squamous intraepithelial lesion/high-grade squamous

intraepithelial lesion [LSIL/HSIL]) and expanded use of the biomarker p16

to classify equivocal lesions as either precancer (HSIL) or low-grade lesions

(LSIL)/non-HPV changes. In one study, among 166 patients with subsequent

pathology (including 131 excisions), 26.2% of p16-positive cases of grade 2

intraepithelial neoplasia versus 4.4% of p16-negative cases were associated with a

subsequent diagnosis of HSIL (-IN 3) or worse (P = 0.002) (64). The results

indicate that using the LAST recommendations would result in

approximately one-third of equivocal (-IN 2) diagnoses being downgraded to

LSIL over 1 year. The significant association of p16 expression with a higher

risk for HSIL on a subsequent specimen suggests that the use of p16 to

adjudicate equivocal (-IN 2) diagnoses in lower anogenital tract specimens as

either LSIL or HSIL would likely predict lesion grade more accurately and

avoid unnecessary excisional procedures. Therefore, strong and diffuse

block-positive p16 results support a categorization of precancerous disease.

Negative or non–block-positive staining strongly favors an interpretation of

low-grade disease or a non–HPV-associated pathology such as immature

squamous metaplasia, atrophy, or reparative changes. Subsequent

publications have confirmed the accuracy of p16 IHC (62,63).

Therefore, women with histologic diagnosis of CIN 2 with negative p16

staining have a very low risk of advancing to CIN 3 and no patient has

developed invasive cancer in these studies. These women can avoid

treatment, especially if they want further childbearing. Postmenopausal

women often have atrophy or reparative changes and they may benefit from

p16 testing as well.

931Colposcopy Findings

Colposcopic assessment is a critical component of the follow-up of the abnormal

cervical screening. Specialty providers in a variety of clinical settings have

historically performed this procedure. In an effort to improve the quality and

consistency of this procedure the American Society of Colposcopy and Cervical

Pathology has developed and disseminated a new set of standards for services in

this arena (59). This process developed standard terminology and definitions of

findings. Table 16-4 summarizes the essential elements of a colposcopic

evaluation.

Acetowhite Epithelium

Epithelium that turns white after application of acetic acid (3% to 5%) is called

acetowhite epithelium (34). The application of acetic acid coagulates the proteins

of the nucleus and cytoplasm and makes the proteins opaque and white (4).

The acetic acid does not affect mature, glycogen-producing epithelium because

the acid does not penetrate below the outer one-third of the epithelium. The cells

in this region have very small nuclei and a large amount of glycogen (not

protein). These areas appear pink during colposcopy. Dysplastic cells are those

most affected. They contain large nuclei with abnormally large amounts of

chromatin (protein). The columnar villi become “plumper” after acetic acid is

applied, making these cells easier to see. They appear slightly white, particularly

in the presence of metaplasia. The immature metaplastic cells have larger nuclei

and show some effects of the acetic acid. Because the metaplastic epithelium is

very thin, it is not as white or opaque as CIN but instead appears gray and filmy

(4).

Leukoplakia

Translated literally, leukoplakia is white plaque (4). This plaque is white

epithelium, visible before application of acetic acid. Leukoplakia represents a

layer of keratin on the surface of the epithelium. Immature squamous epithelial

cells have the potential to develop into keratin- or glycogen-producing cells. In

the vagina and on the cervix, the normal differentiation is toward glycogen.

Leukoplakia should not be confused with the white plaque of a monilial infection,

which can be completely wiped off with a cotton-tipped applicator.

Keratin production is abnormal in the cervicovaginal mucosa. Leukoplakia

results from this process and is commonly associated with HPV infection (Fig.

16-8) and related keratinizing intraepithelial or invasive lesions and should be

biopsied. Other etiologies for this lesion include chronic trauma from diaphragm,

pessary, or tampon use and radiotherapy.

Punctation

932Dilated capillaries terminating on the surface appear from the ends as a collection

of dots and are referred to as punctation (Fig. 16-9). When these vessels occur in

a well-demarcated area of acetowhite epithelium, they indicate an abnormal

epithelium—most often high-grade CIN (Fig. 16-10) (4). The punctate vessels are

formed as the metaplastic epithelium migrates over the columnar villi. Normally,

the capillary regresses; however, when CIN occurs, the capillary persists and

appears more prominent.

Mosaic

Terminal capillaries surrounding roughly circular or polygonal-shaped blocks of

acetowhite epithelium crowded together are called mosaic because of their

appearance (Fig. 16-11). These vessels form a “basket” around the blocks of

abnormal epithelium. They may arise from a coalescence of many terminal

punctate vessels or from the vessels that surround the cervical gland openings (4).

Mosaicism tends to be associated with high-grade lesions (CIN 2 and CIN 3)

(Figs. 16-12 and 16-13).

FIGURE 16-8 Colposcopy of cervical intraepithelial neoplasia 2 (CIN 2) associated with

human papillomavirus (HPV) infection of the cervix.

933The International Federation for Cervical Pathology and Colposcopy published

additional colposcopic criteria for CIN 3. They are ridge sign—dense acetowhite

extending along the cervical ridges, and inner border sign—thick acetowhite with

distinct border existing inside a finer, lacy acetowhite lesion (Fig. 16-14). These

are added to the previously described cuffed gland—dense acetowhite around the

gland openings, and rag sign—peeling of the epithelium in an area of acetowhite

(Fig. 16-15) (65).

Atypical Vascular Pattern

Atypical vascular patterns are characteristic of invasive cervical cancer and

include looped vessels, branching vessels, and reticular vessels.

FIGURE 16-9 Diagram of punctation. The central capillaries of the columnar villi are

preserved and produce the punctate vessels on the surface.

934FIGURE 16-10 Human papillomavirus (HPV)/cervical intraepithelial neoplasia 2 (CIN 2)

presents as a white lesion with surface spicules.

Clinical Pathologic Correlation

[11] It is a best practice for pathologist and colposcopist to jointly review the

colposcopic examination findings, cytology, molecular testing, cervical

biopsy, and endocervical sampling in order to develop a therapeutic plan.

Cytology results should not be sent to one laboratory and the histology results to

another. When the cytology, biopsy, and molecular testing results correlate, the

colposcopist can be reasonably certain that the most clinically significant lesion

was identified. If cytology indicates a more significant lesion than the histology,

the patient may require further evaluation, including repeat colposcopy, additional

biopsies, and excisional diagnostic procedures under certain circumstances.

Management

Clinical Disease Management Guidelines

In 2012, the ASCCP and the NCI sponsored a consensus conference to update

evidence-based guidelines for abnormal cervical cancer screening. This gathering

brought together 47 experts and 23 professional societies, national and

935international health organizations, and federal agencies to review the latest natural

history and clinical data, and consider how the newly updated cervical cancer

screening impacted the clinical follow-up of abnormal screens (66). [12] The new

comprehensive evidence-based guidelines for the management of cervical

cytologic and histologic entities lend themselves to structured clinical

algorithms that are available for download from the Web (www.asccp.org),

on various mobile phone applications, and can be incorporated into a variety

of electronic health record platforms.

CIN 1

[13] Although CIN 1 is a histopathologic manifestation of HPV infection, it is

not a cancer precursor. The spontaneous regression rate of biopsy-proven CIN 1

is conservatively estimated to be 60% to 85% in prospective studies and

regression typically occurs within a 2-year follow-up (4,52,67–70). Patients who

have biopsy-proven CIN 1 (after a cytologic finding of ASC, LSIL) with

satisfactory colposcopy are followed with cytology and high-risk HPV testing

(co-testing) at 12 months. With a negative cytology and high-risk HPV test at the

12-month follow-up these women can be returned to age-appropriate screening.

The patient is returned to colposcopy for appropriate reevaluation in the event of

abnormality on surveillance testing (66). Young women of ages 21 to 24 years in

this clinical scenario may undergo surveillance with repeat cytology only at 12

and 24 months, with referral to colposcopy for ASC-US or greater (66).

[14] For CIN 1 that persists 24 months or more, a patient with an adequate

colposcopic examination may be given the choice of continued surveillance or

destruction of the transformation zone with ablation or excision (66).

However, if colposcopy is inadequate, ablative therapy should be avoided.

Expectant management may not be appropriate for patients with chronic systemic

immunosuppression, such as those requiring steroids, chemotherapy, or

antirejection drugs, and others who may have persistent low-grade abnormalities

(52).

Clinical situations where biopsy histopathology is CIN 1 preceded by ASC-H

or HSIL cytology carry a higher risk. In these settings, follow-up with co-testing

(with cytology and high-risk HPV) at 12 and 24 months or loop excision

procedure may be more appropriate (66).

CIN 2 and CIN 3

Typically, CIN 2 and CIN 3 lesions are neoplastic precursors and grouped for

the purposes of diagnostic reporting and treatment. [14] Women, 25 years of

age and older, with adequate colposcopy and histologic documentation of

CIN 2 and CIN 3 require destruction or excision of the transformation zone

936(66). Ablation should not be considered in cases where colposcopy is inadequate,

CIN 2 and/or 3 is recurrent, or endocervical sampling is positive. This

recommendation is based on a meta-analysis showing that CIN 2 progresses to

CIS in 20% of cases and to invasion in 5%. Progression of CIS to invasion is 5%

(71). Surveillance with co-testing at 12 and 24 months is necessary prior to

returning a patient to routine age-appropriate screening (66).

937938FIGURE 16-11 A: Mosaic pattern and punctation. This pattern develops as islands of

dysplastic epithelium proliferate and push the ends of the superficial blood vessels away,

creating a pattern that looks like mosaic tiles. B: Diagram of mosaic pattern.

There are exceptions to this therapeutic recommendation. The first is among

pregnant women, who in the absence of invasive disease, are followed with

cytology and colposcopy, until reevaluation at 6 weeks postpartum. Additionally,

in recognition of the small but real risk for preterm birth, in young women less

than 25 years of age with CIN 2–3, a program of intensive observation with

colposcopy and cytology is performed at 6 and 12 months, and if normal,

followed by co-testing in another year (66).

FIGURE 16-12 Human papillomavirus (HPV)/cervical intraepithelial neoplasia 3 (CIN 3).

Cribriform pattern of HPV at periphery with mosaicism and punctation near the

squamocolumnar junction.

[15] Although CIN 2–3 can be treated with a variety of outpatient

techniques, the preferred treatment is LEEP. This allows pathologic

evaluation to identify occult microinvasive cancer or adenomatous involvement.

In the latter case, margin status has important prognostic implications. The

939persistent and recurrent disease rate post treatment is estimated at 4% to 10%

(72,73).

Ablative therapy using cryotherapy, laser ablation, or any other technique

is not appropriate when there is CIN 2–3 in the endocervix based on colposcopy

and endocervical curettage (ECC), or evidence of microinvasive or invasive

cancer on cytology, colposcopy, ECC, or biopsy.

FIGURE 16-13 Cervical intraepithelial neoplasia grade 3 (CIN 3).

Cervical Adenocarcinoma In Situ

In adenocarcinoma in situ (AIS), the endocervical glandular cells are replaced by

tall columnar cells with nuclear stratification, hyperchromasia, irregularity, and

increased atypical mitotic activity (74). Cellular proliferation results in crowded,

cribriform glands. The normal branching pattern of the endocervical glands is

preserved. About 50% of women with cervical AIS have squamous CIN 2–3, and

AIS lesions represent incidental findings in specimens removed for treatment of

squamous neoplasia. Usually AIS is located near or above the transformation

zone and conventional cervical specimens may not be effective for detecting

glandular disease. Obtaining good endocervical specimens by Cytobrush may

improve the detection of AIS during the screening process.

940FIGURE 16-14 Colposcopic findings of CIN 3: cuffed gland openings and ridge sign.

[16] AIS is a cancer precursor, and the preferred management for women

who have completed childbearing and have a histologic diagnosis of AIS on a

specimen from a diagnostic excisional procedure is hysterectomy (66). A

histologic diagnosis of AIS from a punch biopsy or a cytologic diagnosis of AIS

is insufficient to justify hysterectomy in the absence of a diagnostic excisional

procedure.

Conservative management with conization can be considered for women

desiring future fertility (66). In such a setting, the status of surgical conization

margins and endocervical sampling at the time of surgery are critical. If either is

positive, reexcision is recommended because of the risk of cancer.

The limits of AIS lesions are difficult to establish by colposcopy or pathology

because of frequent extension of disease within the endocervical canal and the

presence of multifocal, “skip lesions” (i.e., lesions that are not contiguous). For

this reason, negative margins on an excisional specimen may not be entirely

reassuring.

There is good evidence that AIS may progress to invasive cancer (75). In a

study of 40 patients with AIS who had cervical conization, 23 of 40 patients

(58%) had coexisting squamous intraepithelial lesions and 2 had invasive

squamous cell carcinoma (76). Of the 22 patients who underwent hysterectomy,

the margins on the cone specimen were positive in 10 patients, and 70% had

residual AIS, including 2 patients with foci of invasive adenocarcinoma. One of

the 12 patients with negative margins had focal residual adenocarcinoma in the

hysterectomy specimen, and 18 women had conization only with negative

margins and no relapse of disease after a medium interval of 3 years. Thus,

positive margins on the conization specimen are significant findings in these

941patients (77). In a more alarming study of 28 patients with AIS, of the 8 patients

with positive margins who underwent repeat conization or hysterectomy, 3 had

residual AIS and 1 patient had invasive adenocarcinoma (78). Of 10 patients with

negative margins who underwent hysterectomy or repeat conization, 4 had

residual AIS. One patient in whom the cone margin could not be evaluated had

invasive adenocarcinoma. Of the 15 patients treated conservatively with repeat

conization of the cervix and close follow-up, 7 (47%) had a recurrent glandular

lesion detected after the conization, including invasive adenocarcinoma in 2

women. A glandular lesion was not suspected in 48% of the patients, based on

Pap test and ECC results obtained before conization of the cervix.

FIGURE 16-15 Colposcopy findings of CIN 3: rag sign and cuffed gland openings.

In all cases post conization for AIS, recommended surveillance requires

reassessment at 6 months using a combination of cytology, colposcopy, HPV

DNA testing, and endocervical sampling for women who do not undergo

hysterectomy.

Treatment Modalities

Cryotherapy

Cryotherapy destroys the surface epithelium of the cervix by crystallizing the

intracellular water, resulting in the eventual destruction of the cell. The

temperature needed for effective destruction must be in the range of −20° to

−30°C. Nitrous oxide (−89°C) and carbon dioxide (−65°C) produce temperatures

below this range and, therefore, are the most commonly used gases for this

procedure.

942The technique believed to be most effective is a freeze-thaw-freeze method in

which an ice ball is achieved 5 mm beyond the edge of the probe. The time

required for this process is related to the pressure of the gas; the higher the

pressure, the faster the ice ball is achieved. Cryotherapy is an effective treatment

for CIN with very acceptable failure rates under certain conditions (79–82). It is a

relatively safe procedure with few complications. Cervical stenosis is rare but can

occur. Posttreatment bleeding is uncommon and is usually related to infection.

Cure rates are related to the grade of the lesion; CIN 3 has a greater chance of

treatment failure (Table 16-5). Townsend showed that cures are related to the size

of the lesion; those covering most of the ectocervix have failure rates as high as

42%, compared with a 7% failure rate for lesions less than 1 cm in diameter (83).

Positive findings on ECC can reduce the cure rate significantly. Endocervical

gland involvement is important because the failure rate in women with gland

involvement was 27%, compared with 9% in those who did not have such

involvement (84).

Cryotherapy is acceptable when the following criteria are met:

1. CIN 1 that has persisted for 24 months, or CIN 2

2. Small lesion

3. Ectocervical location only

4. Negative endocervical sample

5. No endocervical gland involvement on biopsy

Table 16-5 Results of Cryotherapy for Cervical Intraepithelial Neoplasia (CIN)

Compared With Grade of CIN

Loop Electrosurgical Excision

Loop electrosurgical excision is a valuable tool for the diagnosis and treatment of

CIN (75,85–94). It offers the advantage of performing an operation that is

simultaneously diagnostic and therapeutic during one outpatient visit (95–105).

The tissue effect of electricity depends on the concentration of electrons (size

of the wire), the power (watts), and the water content of the tissue. If low power

or a large-diameter wire is used, the effect will be electrocautery, and the thermal

943damage to tissue will be extensive. If the power is high (35 to 55 W) and the wire

loop is small (0.5 mm), the effect will be electrosurgical, and the tissue will have

little thermal damage. The actual cutting is a result of a steam envelope

developing at the interface between the wire loop and the water-laden tissue. This

envelope is pushed through the tissue, and the combination of electron flow and

acoustical events separates the tissue. After the excision, a 5-mm diameter ball

electrode is used, and the power is set at 50 W. The ball is placed near the surface

so that a spark occurs between the ball and the tissue. This process is called

electrofulguration, and it results in some thermal damage that leads to hemostasis.

If too much fulguration occurs, the patient will develop an eschar with more

discharge, and the risk for infection and late bleeding will be higher.

Loop excision should not typically be used before a high-grade

intraepithelial lesion is identified with histopathology. [17] However,

treatment after an HSIL cytology may be appropriate in certain settings and

among populations for whom colposcopic follow-up is not possible.

LEEP may be associated with an increased risk of overall preterm delivery,

preterm delivery after premature rupture of membranes, and low–birth-weight

infants in subsequent pregnancies at greater than 20 weeks’ gestation (106). The

excision of the entire transformation zone along with varying amounts of the

cervical canal, may compromise birth outcomes (92,94). This is particularly true

for young women, who may have large, immature transformation zones with

extensive acetowhite areas. Complications following loop electrosurgical excision

are relatively minor and compare favorably with those following laser ablation

and conization. Intraoperative hemorrhage, postoperative hemorrhage, and

cervical stenosis can occur but at low rates. The SCJ is visible in more than 90%

of patients after this procedure. Effectiveness of LEEP and comparison of LEEP

to other excision procedures are shown in Tables 16-9 and 16-10.

Conization

Conization of the cervix plays an important role in the management of CIN. It can

be accomplished with a scalpel, electrosurgical needle, or laser. Before the

availability of colposcopy, conization was the standard method of evaluating an

abnormal Pap test result. Conization is a diagnostic and therapeutic procedure and

has the advantage over ablative therapies of providing tissue for further evaluation

to rule out invasive cancer and accurately assess surgical margins

(100,101,103,107).

[18] Conization is indicated for diagnosis in women with CIN 3 or AGC-AIS

and may be considered under the following conditions:

1. Limits of the lesion cannot be visualized with colposcopy.

9442. The SCJ is not evaluable at colposcopy.

3. ECC histologic findings are positive for CIN 2 or CIN 3.

4. Substantial lack of correlation between cytology, biopsy, and colposcopy

results.

5. Microinvasion is suspected based on biopsy, colposcopy, or cytology results.

6. The colposcopist is unable to rule out invasive cancer.

Lesions with positive margins are more likely to recur after conization (Table

16-8) (100,101,103). Endocervical gland involvement is predictive of recurrence

(23.6% with gland involvement compared with 11.3% without gland

involvement) (108). When compared with conization, LEEP is the simpler

technique, and short-term results are similar to those obtained with conization or

laser excision (72,109). In a prospective study examining the long-term effects of

LEEP, conization, and laser excision, no difference in recurrence of dysplasia or

in pregnancy outcomes was found (Tables 16-6 and 16-7) (110).

Hysterectomy

[18] Hysterectomy is the treatment of last resort for recurrent high-grade

CIN. In a study of 38 cases of invasive cancer occurring after hysterectomy

among 8,998 women (0.4%), the incidence of significant bleeding, infection, and

other complications, including death, is higher with hysterectomy than with other

means of treating CIN (76). There are some situations in which hysterectomy

remains a valid and appropriate (although not mandatory) method of treatment for

CIN:

1. Microinvasion

2. Histologically confirmed recurrent high-grade CIN

3. Co-occurring gynecologic pathology requiring hysterectomy, such as fibroids,

prolapse, endometriosis, and pelvic inflammatory disease

Table 16-6 Complications of Electrosurgical Excision

945Table 16-7 Unsuspected Invasion in Electrosurgical Excision Specimens

Table 16-8 Grade of Discomfort of Large Loop Excision Versus Laser Conization

Side Effect Loop Excision (n = 98) Laser (n = 101)

Not unpleasant 80 (92%) 32 (32%)

Moderately unpleasant 16 (16%) 50 (50%)

Very unpleasant 2 (2%) 19 (18%)

Operative time 20–50 sec 4–15 min

(mean, 16 sec) (mean, 6.5 min)

946From Gunasekera PC, Phipps JH, Lewis BV. Large loop excision of the transformation

zone (LLETZ) compared to carbon dioxide laser in the treatment of CIN: a superior mode

of treatment. Br J Obstet Gynaecol 1990;97:995–998, with permission.

Table 16-9 Results of Loop Electrosurgical Excision

Author (Ref. No.) Patients Treated Patients Recurred

Prendiville et al. (85)

102

2

Whiteley and Olah (86)

80

4

Bigrigg et al. (87)

1,000

41

Gunasekera et al. (88)

98

7

Luesley et al. (92)

616

27

Murdoch et al. (93)

600

16

Total

2,496 97 (3.9%)

Table 16-10 Recurrence of Cervical Intraepithelial Neoplasia After Cone Biopsy

VAGINAL INTRAEPITHELIAL NEOPLASIA

Vaginal intraepithelial neoplasia (VAIN) often accompanies CIN and shares a

947common etiology (111). Such lesions may be extensions onto the vagina from the

CIN, or they may be satellite lesions occurring mainly in the upper vagina.

Because the vagina does not have a transformation zone with immature epithelial

cells to be infected by HPV, the mechanism of entry for HPV is by way of

microabrasions resulting primarily from insertional sexual activity. As these

abrasions heal with metaplastic squamous cells, the HPV may begin its growth in

a manner similar to that in the cervical transformation zone. VAIN lesions are

asymptomatic. Because they often accompany active HPV infection, the patient

may report vulvar warts or an odoriferous vaginal discharge from vaginal warts.

Diagnosis

Women with an intact cervix should undergo routine cytologic screening. VAIN

is nearly always accompanied by CIN and cytology is likely to be positive when

VAIN is present. The vagina should be carefully inspected by colposcopic

examination at the time of colposcopy for any CIN lesion. Particular attention

should be paid to the upper vagina. Women who have persistent abnormal

cytology without evident cervical pathology and those with abnormal

cytology after treatment of CIN should be examined carefully for VAIN. For

women in whom the cervix was removed for high-grade cervical neoplasia, Pap

testing should be performed at regular intervals (e.g., yearly), depending on the

diagnosis and severity of lesion.

Colposcopic examination and directed biopsy are the mainstays of diagnosis of

VAIN. Typically, the lesions are located along the vaginal ridges, are ovoid in

shape and slightly raised, and often have surface spicules. VAIN 1 lesions usually

are accompanied by a significant amount of koilocytosis, indicating their HPV

origin (Fig. 16-16). VAIN 2 exhibits a thicker acetowhite epithelium, a more

raised external border, and less iodine uptake (Fig. 16-17A). When VAIN 3

occurs, the surface may become papillary, and the vascular patterns of punctation

and mosaic may occur (Fig. 16-17B). Early invasion is typified by vascular

patterns similar to those of the cervix.

948FIGURE 16-16 Human papillomavirus (HPV)/vaginal intraepithelial neoplasia grade 1

(VAIN 1). Note the surface spicules with partial uptake of Lugol’s stain.

Treatment

[19] Patients with VAIN 1/HPV or VAIN 2 do not require treatment and

may be managed with surveillance. These lesions often regress, are multifocal,

and recur quickly when treated with ablative therapy. VAIN 3 lesions are more

likely to be associated with early invasive disease. In a study of 32 patients who

underwent upper vaginectomy for VAIN 3, occult invasive carcinoma was found

in 9 patients (28%) (112). It is recommended in older patients that VAIN 3

lesions located in the dimples of the vaginal cuff be excised to rule out occult

invasive cancer. [19] VAIN 3 lesions that are adequately sampled to rule out

invasive disease can be treated with laser therapy or excisional therapy. The

major advantage of laser vaporization therapy is the ability to control the

depth and width of destruction by direct vision through the colposcope. The

other advantage of laser therapy is the rapid posttreatment healing phase. This

process takes about 3 to 4 weeks, after which time a new epithelium has formed

completely and, in most cases, has a mature glycogen-containing epithelium.

Tissue Interaction

949When the laser beam contacts tissue, its energy is absorbed by the water in the

cells, causing it to boil instantly. The cells explode into a puff of vapor (thus the

term laser vaporization). The protein and mineral content are incinerated by the

heat and leaves a charred appearance at the base of the exposed area. The depth of

laser destruction is a function of the power of the beam (in watts), the area of the

beam (in millimeters squared), and the length of time the laser remains in the

tissue. The beam must be moved uniformly across the tissue surface to prevent

deep destruction. The laser beam vaporizes a central area and leaves a narrow

zone of heat necrosis surrounding the laser crater. The goal of laser vaporization

is to minimize the area of tissue necrosis. This goal is accomplished by using high

wattage (20 W) with medium beam size (1.5 mm) and moving the beam

uniformly but quickly over the surface. The zone of thermal necrosis will be 0.1

mm when the laser is used in this manner. Some lasers have a function called

super pulse, in which the laser beam is electronically switched off and on

thousands of times per second, thereby allowing the tissue to cool between pulses

to create less thermal necrosis.

950951FIGURE 16-17 A: Vaginal intraepithelial neoplasia grade 2 (VAIN 2). B: Vaginal

intraepithelial neoplasia grade 3 (VAIN 3).

Cryosurgery should not be used in the vagina because the depth of injury

cannot be controlled and inadvertent injury to the bladder or rectum may occur.

Superficial fulguration with electrosurgical ball cautery may be used under

colposcopic control to observe the depth of destruction by wiping away the

epithelial tissue as it is ablated. Excision is an excellent method for treatment of

upper vaginal lesions in a small area. Occasionally, total vaginectomy will be

required for a VAIN 3 lesion occupying the entire vagina. It should be

accompanied by a split-thickness skin graft. This aggressive treatment for

widespread vaginal lesions should not be used for VAIN 2.

The malignant potential of VAIN appears to be less than that of CIN. In a

review of 136 cases of CIS of the vagina over a 30-year period, 4 cases (3%)

progressed to invasive vaginal cancer despite the use of various treatment

methods (111).

VULVAR INTRAEPITHELIAL DISEASE

Vulvar Dystrophies

In the past, terms such as leukoplakia, lichen sclerosis et atrophicus, primary

atrophy, sclerotic dermatosis, atrophic and hyperplastic vulvitis, and kraurosis

vulvae were used to denote disorders of epithelial growth and differentiation

(113). In 1966, Jeffcoate suggested that these terms did not refer to separate

disease entities because their macroscopic and microscopic appearances were

variable and interchangeable (114). He assigned the generic term chronic vulvar

dystrophy to the entire group of lesions.

The International Society for the Study of Vulvar Disease (ISSVD)

recommended that the old dystrophy terminology be replaced by a new

classification under the pathologic heading nonneoplastic epithelial disorders of

skin and mucosa. This classification is shown in Table 16-11. In all cases,

diagnosis requires biopsy of suspicious-looking lesions, which are best detected

by careful inspection of the vulva in a bright light aided, if necessary, by a

magnifying glass (115).

The malignant potential of these nonneoplastic epithelial disorders is low, and

lesions with atypia are classified as vulvar intraepithelial neoplasia (VIN).

Patients with lichen sclerosis and concomitant hyperplasia may be at particular

risk (116).

Vulvar Intraepithelial Neoplasia

952As with the vulvar dystrophies, there is confusion regarding the nomenclature for

VIN. Four major terms are used: erythroplasia of Queyrat, Bowen disease,

carcinoma in situ simplex, and Paget disease. In 1976, the ISSVD decreed that

the first three lesions were merely gross variants of the same disease process and

that all of these entities should be included under the umbrella term squamous cell

carcinoma in situ (stage 0) (92). In 1986, the ISSVD recommended the term

vulvar intraepithelial neoplasia (Table 16-11).

Table 16-11 Classification of Epithelial Vulvar Diseases

Nonneoplastic epithelial disorders of the skin and mucosa

Lichen sclerosis (lichen sclerosis et atrophicus)

Squamous hyperplasia (formerly hyperplastic dystrophy)

Other dermatoses

Mixed nonneoplastic and neoplastic epithelial disorders

Intraepithelial neoplasia

Squamous intraepithelial neoplasia

VIN 1

VIN 2

VIN 3 (severe dysplasia or carcinoma in situ)

Nonsquamous intraepithelial neoplasia

Paget disease

Tumors of melanocytes, noninvasive

Invasive tumors

VIN, vulvar intraepithelial neoplasia.

From Committee on Terminology, International Society for the Study of Vulvar

Disease. New nomenclature for vulvar disease. Int J Gynecol Pathol 1989;8:83, with

permission.

VIN is graded as 1 (mild), 2 (moderate), or 3 (severe or CIS) on the basis of

cellular immaturity, nuclear abnormalities, maturation disturbance, and mitotic

activity. In VIN 1, immature cells, cellular disorganization, and mitotic activity

occur predominantly in the lower one-third of the epithelium, whereas in VIN 3,

immature cells with scanty cytoplasm and severe chromatinic alterations occupy

most of the epithelium (Fig. 16-18). Dyskeratotic cells and mitotic figures occur

in the superficial layer. The appearance of VIN 2 is intermediate between VIN 1

and VIN 3. Additional cytopathic changes of HPV infection, such as perinuclear

953halos with displacement of the nuclei by the intracytoplasmic viral protein,

thickened cell borders, binucleation, and multinucleation, are common in the

superficial layers of VIN, especially in VIN 1 and VIN 2. These viral changes are

not definitive evidence of neoplasia but are indicative of viral exposure (117).

Most vulvar condylomas are associated with HPV-6 and -11, whereas HPV-16 is

detected in more than 80% of VIN cases by molecular techniques.

[20] VIN 3 is a neoplastic precursor and can be unifocal or multifocal.

Typically, multifocal VIN 3 presents with small hyperpigmented lesions on the

labia majora (Fig. 16-19). Some cases of VIN 3 are more confluent, extending to

the posterior fourchette and involving the perineal tissues. The term bowenoid

papulosis (bowenoid dysplasia) was used to describe multifocal VIN lesions

ranging from grade 1 to 3. Clinically, patients with bowenoid papulosis present

with multiple small pigmented papules (40% of cases) that are usually less than 5

mm in diameter. Most women with these lesions are in their 20s, and some are

pregnant. After childbirth, the lesions may regress spontaneously. The term

bowenoid papulosis is no longer recommended by the ISSVD.

The American College of Obstetrics and Gynecology published a committee

opinion on the management of VIN (118). The report indicates that VIN 1 is no

longer considered a precancerous lesion. It is most often an HPV lesion or

may be overcalled, and does not require treatment. VIN 2 with p16 positive

should be treated in the same manner as VIN 3. VIN 2 lesions with negative

p16 can be observed.

VIN Treatment

The treatment of VIN 3 varies from wide excision to the performance of a

superficial or “skinning” vulvectomy (119–122). Although the treatment

originally recommended for CIS of the vulva was wide excision, fears that the

disease is preinvasive led to the widespread use of superficial vulvectomy (121).

Because progression is relatively uncommon, typically occurring in 5% to 10% of

cases, extensive surgery is not warranted (119). This is particularly important

because many VIN 3 lesions are found in premenopausal women.

The therapeutic alternatives for VIN 3 are simple excision, laser ablation,

and superficial vulvectomy with or without split-thickness skin grafting.

Excision of small foci of disease produces excellent results and has the advantage

of providing a histopathologic specimen. Although multifocal or extensive lesions

may be difficult to treat by this approach, it offers the potential for the most

cosmetic result. Repeat excision is often necessary but can usually be

accomplished without vulvectomy (120,122).

954FIGURE 16-18 Carcinoma in situ of the vulva (vulvar intraepithelial neoplasia grade 3,

VIN 3).

The carbon dioxide laser can be used for multifocal lesions but is unnecessary

for unifocal disease. The disadvantages are that it can be painful and costly and

does not provide a histopathologic specimen (123).

Superficial vulvectomy is appropriate to treat extensive and recurrent VIN 3

(122). The goal of the surgery is to extirpate all of the disease while preserving as

much of the normal vulvar anatomy as possible. The anterior vulva and the

clitoris should be preserved if possible. In some patients, the disease extends up

the anus, which must be resected. An effort should be made to close the vulvar

defect primarily, reserving the use of skin grafts for instances in which the vulvar

defect cannot be closed because the resection is so extensive. Split-thickness skin

grafts can be harvested from the thighs or buttocks, but the latter is more easily

concealed (124).

Paget Disease of the Vulva

Extramammary Paget disease of the vulva (AIS) was described 27 years after the

description by Sir James Paget of the mammary lesion that now bears his name

955(125). Some patients with vulvar Paget disease have an underlying

adenocarcinoma, although the precise frequency is difficult to ascertain.

FIGURE 16-19 Vulvar carcinoma in situ: carcinoma in situ (VIN 3) extending into the

hair follicle.

956FIGURE 16-20 Paget disease of the vulva. The epidermis is permeated by abnormal cells

with vacuolated cytoplasm and atypical nuclei. This heavy concentration of abnormal cells

in the parabasal layers is typical of Paget disease.

Histology

Most cases of vulvar Paget disease are intraepithelial. Because these lesions

demonstrate apocrine differentiation, the malignant cells are believed to arise

from undifferentiated basal cells, which convert into an appendage type of cell

during carcinogenesis (Fig. 16-20). The “transformed cells” spread

957intraepithelially throughout the squamous epithelium and may extend into the

appendages. In most patients with an underlying invasive carcinoma of the

apocrine sweat gland, Bartholin gland, or anorectum, the malignant cells are

believed to migrate through the dermal ductal structures and reach the epidermis.

In such cases, metastasis to the regional lymph nodes and other sites can occur.

Paget disease must be distinguished from superficial spreading melanoma. All

sections should be studied thoroughly using differential staining, particularly

periodic acid–Schiff (PAS) and mucicarmine stains. Mucicarmine has routinely

positive results in the cells of Paget disease and negative results in melanotic

lesion.

Clinical Features

Paget disease of the vulva predominantly affects postmenopausal white women,

and the presenting symptoms are usually pruritus and vulvar soreness. The lesion

has an eczematoid appearance macroscopically and usually begins on the hairbearing portions of the vulva (Fig. 16-21). It may extend to involve the mons

pubis, thighs, and buttocks. Extension to the mucosa of the rectum, vagina, or

urinary tract is described (126). The more extensive lesions are usually raised and

velvety in appearance.

A second synchronous or metachronous primary neoplasm is associated with

extramammary Paget disease in about 4% of patients, which is much less

common than previously believed (127). Associated carcinomas were reported in

the cervix, colon, bladder, gallbladder, and breast. When the anal mucosa is

involved, there usually is an underlying rectal adenocarcinoma (116).

Treatment

Unlike squamous cell VIN 3, in which the histologic extent of disease correlates closely

with the macroscopic lesion, Paget disease usually extends well beyond the gross lesion

(128). This extension results in positive surgical margins and frequent local recurrence

unless a wide local excision is performed (129). Underlying adenocarcinomas are

apparent clinically, but this finding does not occur invariably; therefore, the underlying

dermis should be removed for adequate histologic evaluation. For this reason, laser

therapy is unsatisfactory in treating primary Paget disease. If underlying invasive

carcinoma is present, it should be treated in the same manner as a squamous vulvar

cancer. This treatment usually requires radical vulvectomy and at least an ipsilateral

inguinal–femoral lymphadenectomy.

958FIGURE 16-21 Paget disease of the labium majus.

Recurrent lesions are almost always in situ, although there was at least one

report of an underlying adenocarcinoma in recurrent Paget disease (127). It is

reasonable to treat recurrent lesions with surgical excision.

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